Clinical case of multiple metachronous intraorbital arteriovenous fistulas in a patient with congenital heart disease
https://doi.org/10.17650/1683-3295-2024-26-4-81-87
Abstract
Intraorbital arteriovenous fistulas are rare arteriovenous shunts inside the orbit without connection with the cavernous sinus. This article describes a clinical case of multiple metachronous intraorbital arteriovenous shunts in a patient with univentricular heart disease and secondary erythrocytosis. Transarterial embolization of the first shunt had a positive clinical effect for 2 months. The recurrence of symptoms was caused by the formation of a new shunt on the same draining vein, but in a place remote from the previous locus. Repeated embolization gave a positive effect for the same period. The next relapse had a more malignant course, up to dislocation of the eyeball. The right orbit decompression has given a stable positive clinical effect up to the present moment. Based on extremely limited literature data of such cases and our own experience, we concluded that an individual and multidisciplinary approach to such patients with careful postoperative follow-up is necessary.
Keywords
About the Authors
A. A. GlushaevaRussian Federation
Alexandra Andreevna Glushaeva
630055; 15 Rechkunovskaya St.; Novosibirsk
D. S. Kislitsin
Russian Federation
630055; 15 Rechkunovskaya St.; Novosibirsk
T. S. Shayakhmetov
Russian Federation
630055; 15 Rechkunovskaya St.; Novosibirsk
M. G. Kilchukov
Russian Federation
630055; 15 Rechkunovskaya St.; Novosibirsk
R. S. Kiselyov
Russian Federation
630055; 15 Rechkunovskaya St.; Novosibirsk
A. V. Gorbatykh
Russian Federation
630055; 15 Rechkunovskaya St.; Novosibirsk
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Review
For citations:
Glushaeva A.A., Kislitsin D.S., Shayakhmetov T.S., Kilchukov M.G., Kiselyov R.S., Gorbatykh A.V. Clinical case of multiple metachronous intraorbital arteriovenous fistulas in a patient with congenital heart disease. Russian journal of neurosurgery. 2024;26(4):81-87. (In Russ.) https://doi.org/10.17650/1683-3295-2024-26-4-81-87